vWF structure and functional analysis of A1,A2 ,A3 domains

Von Willebrand factor (vWF) is a multimeric plasmaGPIbα is the largest subunit within the complex and
glycoprotein that mediates platelet adhesion to theis the only subunit implicated in ligand binding. The
subendothelium at sites of vascular injury.ligand-binding region resides within approximately 300
Platelets are cytoplasmic fragments of megaamino acids at the GPIbα N terminus . The
karyocytes and, therefore, their membrane proteinsligand-binding region can be divided into three distinct
cannot be manipulated by expression methods instructural sub domains that are mixed in vWF binding
culture. Platelets participate in the physiologicincluding seven tandem leucine-rich repeats, disulfide
mechanisms that interrupt bleeding a process calledloops flanking the leucine-rich repeats, and a highly
hemostasis by adhering to injured vascular surfacesnegatively charged sequence spanning residues
and aggregating with one another. The pathologicalAsp-269 to Asp-287 . Three tyrosine residues
counterpart of this normal activity is the occurrence(Tyr-276, Tyr-278, and Tyr-279) are embedded in
of arterial thrombosis, caused by the formation ofthis negatively charged sequence  and each is fully
thrombi that occlude atherosclerotic vessels andsulfated .
curtail blood supply to organs. Central to the function 
of platelets is the interaction of adhesive molecules inIt does so by forming a link between specific platelet
the vessel wall and blood with receptor glycoproteinsmembrane receptors and constituents of the
on the outer plasma membrane .subendothelial connective tissue. In addition, vWF
GPIb serves as one of the essential receptors forbinds to and stabilizes blood coagulation factor VIII in
von Willebrand factor (vWF) and plays a crucial role inthe circulation. vWF is synthesized from an 8.7-kb
platelet thrombus formation. Undeniably, the bindingmRNA and appears to be expressed exclusively in
of multimeric vWF to GPIb results in plateletendothelial cells ECs and megakaryocytes. vWF is
activation and may lead to adhesion and aggregation .commonly used as an immunohistochemical marker
GPIbα is also a classical oncoprotein in which itsfor ECs. vWF is a long protein which contained many
deregulated expression leads to transformation,domains and each domain meant for a significant
reduced growth factor requirements, increasedfunctions. Here we have analyzed the structure and
resistance to apoptosis. GPIbα also promotesfunctions of A1, A2 and A3 domains of vWf in
double-stranded DNA breaks, and induces profounddetails. Furthermore, we found that vWF is directly
nuclear dysmorphology, indicating that, in addition toassociated a large number of disease, that are
its direct transforming function, it also displaysknown as von Willebrand disease. The expression of
genotoxicity at several distinct levels.the murine vWF gene usually downregulated by LPS
GPIbα contributes to arterial thrombosis by adhesionin many tissues. Domain A identifies a superfamily of
mechanisms independent of the binding to vWF.proteins involved in biological processes controlled by
Platelet adhesion to the extracellular matrix (ECM) is aspecific molecular interactions, often adhesive in
key step in thrombus formation as found innature which interacts with cell surface receptor
hemostasis and thrombosis. The interaction ofintegrin. vWF is known to perform a large number of
platelet receptor GPIbα and vWF exposed in thefunctions in human body including cell surface
extracellular matrix is commonly accepted as the keyreceptor binding, blood coagulation and maintaining
event required for the initial tethering of plateletsbody stress.
along the damaged vascular wall, especially underWhen the endothelium is disrupted, vWF binds to
conditions of high shear stress . The GPIb-V-IXcollagen of the sub endothelium. In areas of low
receptor complex consists of four gene products,blood flow rate, platelets may adhere to vessel walls
GPIbα, GPIbβ, GPIX, and GPV (Lopez JA, 1994).independently of vWF. In areas with a high blood
Approximately 25,000 copies of GPIb-IX and 12,000flow rate, vWF is necessary for the platelets to
copies of GPV are expressed on resting platelets.adhere to the sub endothelium. Although some vWF
The ligand-binding site for vWF is located within theis located in the sub endothelium, additional vWF is
45-kDa N-terminal region of GPIbα.needed for an optimal platelet adhesion. In such
GPIb-V-IX complex plays an important role in vascularinstances, additional vWF is released from platelet or
biology. It is involved in the interaction betweenendothelial cell granules. As vWF binds to exposed
resting platelets and activated leukocytes by itscollagen, its conformation changes allowing an
binding to Mac-1  and activated endothelial cells by itsincreased binding affinity for glycoprotein Ib located
binding to P-selectin. GPIbα also interacts withon the platelet membrane. Platelets subsequently bind
thrombin , high molecular weight kininogen, coagulationto vWF and adhere to the vessel wall. Once the
factors XI and XII, and TSP-1 . On binding of a ligandplatelets are activated, they expose their
the GPIb-V-IX receptor complex induces signalsfibrinogen-binding sites (glycoprotein IIb-IIIa).
leading to calcium mobilization, rearrangement of theFibrinogen adheres and further aggregation of
cytoskeleton, granule release, and activation ofplatelets occurs. vWF may also bind to platelets to
αIIbβ3 integrin .stabilize their attachment.
The importance of the GPIb-V-IX receptor forThe crystal structure of all three domains is
hemostasis is shown by the strong bleeding diathesisdetermined and interestingly, all three domains share
found in Bernard–Soulier syndrome (BSS) patientsidentical three dimensional fold with a-b-a sandwiched
lacking the GPIb-V-IX complex on the platelet surfacemodel.  Here we have extensively studied the clinical
or in patients lacking VWF.significance of vWF with respect to its functions and
Glycoprotein Ibα (GP Ibα), the ligand binding subunitstructure. We hope that this review may be a
of the platelet glycoprotein Ib-IX-V complex, isvaluable to for researcher who are working in the
sulfated on three tyrosine residues (Tyr-276,similar field.
Tyr-278, and Tyr-279).